Spindle cell hemangioma in the infratemporal fossa: A unique case report. (January 2021)

• Record Type: Journal Article
• Authors: Oukessou, Y.; Lyoubi, M.; Hammouda, Y.; Rouadi, S.; Abada, R.L.; Roubal, M.; Mahtar, M.
• Is Part Of: International journal of surgery case reports. Volume 78(2021)
• Page Start: 38
• Page End: 41
• Publication Date: 2021-01
• Subjects: Spindle cell -- Hemangioma -- Infratemporal fossa -- Case report; Surgery -- Periodicals; Surgical Procedures, Operative -- Periodicals; Surgery; Electronic journals; Periodicals; 617.005
• DOI: 10.1016/j.ijscr.2020.11.147
• Languages: English
• ISSNs: 2210-2612

Abstract

Highlights: Spindle cell hemangioma (SCH) is a rare vascular tumor that was considered to be intermediate -or low-grade malignancy, with biological behavior between a hemangioma and angiosarcoma. The SCH is commonly found in the distal extremities. So far, only 16 cases have been described in the head and neck area. No previous case has been described in the infratemporal fossa. SCH shows a proliferation of spindle cells composed of endothelial cells, pericytes and fibroblasts between dilated vascular spaces and immunoreactivity to endothelial markers. Abstract: Introduction: Spindle cell hemangioma (SCH) is a rare vascular tumor which was first described in 1986. It affects mostly the distal extremities. The head and neck are rarely involved. This article reports the first case of SCH in the infratemporal fossa. Presentation of case: A 41-year-old woman presented with an 8-month history of right cheek swelling. Facial CT scan and MRI showed an intensely and heterogeneously enhancing tumor of the infratemporal fossa suggesting an angiomatous neoplasm. The mass was excised surgically through an anterior maxillary approach. The histopathological and immunohistochemistry analysis revealed a SCH. Conclusion: This case report presents a unique presentation of a Spindle cell hemangioma in an unexpected location of the head and neck region. it underlines the importance for clinicians and pathologists to consider the Spindle cell hemangioma as a possible etiological diagnosis of infratemporal fossa tumors.