Atypical multiple simple bone cysts in the maxilla and mandible. Issue 2 (March 2023)

• Record Type: Journal Article
• Authors: Hoshino, Teruhide; Yoshida, Shuji; Katakura, Akira
• Is Part Of: Journal of oral and maxillofacial surgery, medicine, and pathology. Volume 35:Issue 2(2023)
• Page Start: 178
• Page End: 183
• Publication Date: 2023-03
• Subjects: Simple bone cyst -- Atypical bone cyst -- Biopsy -- Radiolucent lesion; Mouth -- Surgery -- Periodicals; Face -- Surgery -- Periodicals; Maxilla -- Surgery -- Periodicals; Oral medicine -- Periodicals; Mouth -- Diseases -- Pathogenesis -- Periodicals; Surgery, Oral -- Periodicals; Oral Medicine -- Periodicals; Pathology, Oral -- Periodicals; Face -- Surgery; Maxilla -- Surgery; Mouth -- Diseases -- Pathogenesis; Mouth -- Surgery; Oral medicine; Electronic journals -- Sciences; Electronic journals -- Medicine; Periodicals; 617.522059
• DOI: 10.1016/j.ajoms.2022.08.008
• Languages: English
• ISSNs: 2212-5566

Abstract

Abstract: Here we report a rare case of a 46-year-old female with multiple simple bone cysts (SBC) with recurrence as noted by the appearance of new lesions during a routine follow-up. The patient visited a dental clinic for a toothache in 2008, and panoramic radiography revealed mixed radiolucent-radiodense lesions with well-defined borders in the mandibular first and second molar sites bilaterally. An intra-oral examination performed at our institute in July 2019 revealed no apparent swelling on either side of the mandible and no gingival or oral mucosa abnormalities. Panoramic radiography revealed radiolucent lesions with well-defined borders in the bilateral mandibular molar region. Biopsy was performed under local anesthesia and no evidence of an epithelial lining was found in the specimens obtained from either side of the jaw, suggesting a diagnosis of SBC; therefore, curettage was performed in the surrounding bone. One year post-surgery, a new lesion was observed in the left upper first molar region; consequently, curettage was performed. Histopathological examination once again suggested SBC. Six months later, relapse was observed on the right side of the mandible. Curettage was performed in September 2021, and there has been no evidence of recurrence and no clinical symptoms. Based on this case, we concluded that it is essential to counsel patients on the necessity of periodic follow-up with imaging and raise awareness regarding the risk of recurrence of SBC.